Franceschini G, Sirtori C R, Capurso A, Weisgraber K H, Mahley R W
J Clin Invest. 1980 Nov;66(5):892-900. doi: 10.1172/JCI109956.
Significant hypertriglyceridemia with a very marked decrease of high density lipoproteins (HDL)-cholesterol levels (7-14 mg/dl) was detected in three members (father, son, and daughter) of an Italian family. The three affected individuals did not show any clinical signs of atherosclerosis, nor was the atherosclerotic disease significantly present in the family. Lipoprotein lipase and lecithin:cholesterol acyltransferase activites were normal or slightly reduced. Morphological and compositional studies of HDL in the subjects showed a significant enlargement of the lipoprotein particles (approximately 120 vs. approximately 94 A for control HDL) and a concomitant increase in the triglyceride content. Analytical isoelectric focusing of HDL apoproteins provided evidence for multiple isoproteins in the apoprotein(apo)-A-I range, with nine different bands being detected instead of the usual four bands observed in normal subjects. Two-dimensional immunoelectrophoresis against apo-A antiserum indicated a clear reduction of apo-A in the alpha electrophoretic region, with splitting of the protein "peak." The observation in otherwise clinically healthy subjects of hypertriglyceridemia, reduced HDL-cholesterol, and marked apoprotein abnormalities, without a significant incidence of atherosclerotic disease in the family suggests this is a new disease entity in the field of lipoprotein pathology, very probably related to an altered amino acid composition of the apo-A-I protein (see Weisgraber et al. 1980. J. Clin. Invest. 66: 901-907).
在一个意大利家庭的三名成员(父亲、儿子和女儿)中检测到显著的高甘油三酯血症,同时高密度脂蛋白(HDL)胆固醇水平显著降低(7 - 14毫克/分升)。这三名受影响的个体未表现出任何动脉粥样硬化的临床症状,且该家族中动脉粥样硬化疾病也不显著。脂蛋白脂肪酶和卵磷脂胆固醇酰基转移酶活性正常或略有降低。对这些受试者HDL的形态学和成分研究显示,脂蛋白颗粒显著增大(对照HDL约为94埃,而受试者的约为120埃),同时甘油三酯含量增加。HDL载脂蛋白的分析等电聚焦显示在载脂蛋白(apo)-A-I范围内存在多种同型蛋白,检测到九条不同的条带,而正常受试者通常观察到四条条带。针对apo-A抗血清的二维免疫电泳表明,α电泳区域的apo-A明显减少,蛋白质“峰”出现分裂。在临床健康的受试者中观察到高甘油三酯血症、HDL胆固醇降低和明显的载脂蛋白异常,而该家族中动脉粥样硬化疾病的发生率并不显著,这表明这是脂蛋白病理学领域的一种新的疾病实体,很可能与apo-A-I蛋白的氨基酸组成改变有关(见Weisgraber等人,1980年。《临床研究杂志》66: 901 - 907)。