Han Y M, Lee D K, Lee S Y, Chung K H, Kim M H, Sohn M H, Kim C S, Choi K C
Department of Diagnostic Radiology, Chonbuk National University Medical School, Chonju City, Republic of Korea.
J Korean Med Sci. 1994 Feb;9(1):86-91. doi: 10.3346/jkms.1994.9.1.86.
Adult presentation of congenital cystic adenomatoid malformation(CCAM) of the lung is so rare that only 5 cases have been reported in the literature to date. We report the case of a 19-year-old female with CCAM in the left lower lobe. Computed tomography showed a multilobulated cystic lesion with multiple air-fluid levels and also showed focal enhancement of the solid component in the eccentrical portion of the lesion. Thoracic aortogram and selected bronchial arteriograms show a slightly enlarged and tortuous bronchial artery feeding the multilobulated cystic lesion. We present the clinical and radiological features of our case with a brief review of the literature.
成人先天性肺囊性腺瘤样畸形(CCAM)的表现极为罕见,迄今为止文献中仅报道过5例。我们报告了一名19岁左下叶患有CCAM的女性病例。计算机断层扫描显示一个多叶的囊性病变,有多个气液平面,病变偏心部分的实性成分有局灶性强化。胸部主动脉造影和选择性支气管动脉造影显示,为多叶囊性病变供血的支气管动脉略有增粗和迂曲。我们结合文献简要回顾,介绍了该病例的临床和放射学特征。