Albrecht S, Schneider M C, Belmont J, Armstrong D L
Department of Pathology Neuropathology, Baylor College of Medicine, Houston, Texas.
Acta Neuropathol. 1993;85(4):394-9. doi: 10.1007/BF00334450.
We report three siblings born with severe neonatal encephalopathy, manifested clinically by microcephaly, myoclonus, and muscular hypertonus. Karyotypic analyses and all biochemical investigations were unrevealing. All three patients died during infancy. Postmortem examination of the brain in one child disclosed severe neuronal loss in the inferior olives and the pontine nuclei. There was also severe hypoplasia of the cerebellum and micrencephaly. There was diffuse gliosis of the white matter in all areas of the brain. We believe this may represent a previously undescribed form of familial infantile encephalopathy with olivopontocerebellar hypoplasia.
我们报告了三例患有严重新生儿脑病的同胞兄弟姐妹,临床表现为小头畸形、肌阵挛和肌肉张力亢进。染色体核型分析和所有生化检查均无异常发现。三名患者均在婴儿期死亡。对其中一名患儿进行的脑死后检查显示,下橄榄核和脑桥核有严重的神经元丢失。小脑也有严重发育不全和脑过小。大脑所有区域的白质均有弥漫性胶质增生。我们认为这可能代表一种以前未描述过的伴有橄榄脑桥小脑发育不全的家族性婴儿脑病形式。