Peretz H, Mulai A, Usher S, Zivelin A, Segal A, Weisman Z, Mittelman M, Lupo H, Lanir N, Brenner B, Shpilberg O, Seligsohn U
Institute of Thrombosis and Hemostasis, Department of Hematology, Chaim Sheba Medical Center, Tel-Hashomer, Israel.
Blood. 1997 Oct 1;90(7):2654-9.
Previous studies showed that factor XI (FXI) deficiency commonly observed in Ashkenazi Jews is caused by two similarly frequent mutations, type II (Glu117stop) and type III (Phe283Leu) with allele frequencies of 0.0217 and 0.0254, respectively. In Iraqi Jews, who represent the ancient gene pool of Jews, only the type II mutation was observed with an allele frequency of 0.0167. In this study we sought founder effects for each mutation by examination of four FXI gene polymorphisms enabling haplotype analysis in affected Jewish patients of Ashkenazi, Iraqi, and other origins and in Arab patients. Initial population surveys of 387 Middle Eastern Jews (excluding Iraqi Jews), 560 North African/Sephardic Jews, and 382 Arabs revealed allele frequencies for the type II mutation of 0.0026, 0.0027, and 0.0065, respectively. In contrast, the type III mutation was not detected in any of these populations. All 60 independent chromosomes bearing the type III mutation were solely observed in Ashkenazi Jewish patients and were characterized by a relatively rare haplotype. All 103 independent chromosomes bearing the type II mutation in patients of Ashkenazi, Iraqi, Yemenite, Syrian, and Moroccan Jewish origin and of Arab origin were characterized by another distinct haplotype that was rare among normal Ashkenazi Jewish, Iraqi Jewish, and Arab chromosomes. These findings constitute the first example of a mutation common to Ashkenazi Jews, non-Ashkenazi Jews, and Arabs and are consistent with the origin of type II mutation in a founder before the divergence of the major segments of Jews. Our findings also indicate that the type III mutation arose more recently in an Ashkenazi Jewish individual.
先前的研究表明,在德系犹太人中常见的因子XI(FXI)缺乏症是由两种频率相近的突变引起的,即II型(Glu117stop)和III型(Phe283Leu),其等位基因频率分别为0.0217和0.0254。在代表犹太人古老基因库的伊拉克犹太人中,仅观察到II型突变,其等位基因频率为0.0167。在本研究中,我们通过检测四种FXI基因多态性来寻找每种突变的奠基者效应,这些多态性能够对德系、伊拉克及其他血统的犹太裔患者以及阿拉伯裔患者进行单倍型分析。对387名中东犹太人(不包括伊拉克犹太人)、560名北非/西班牙裔犹太人和382名阿拉伯人的初步群体调查显示,II型突变的等位基因频率分别为0.0026、0.0027和0.0065。相比之下,在这些群体中均未检测到III型突变。所有携带III型突变的60条独立染色体仅在德系犹太患者中观察到,并且具有相对罕见的单倍型。所有103条携带II型突变的独立染色体,其来源包括德系、伊拉克、也门、叙利亚和摩洛哥犹太裔患者以及阿拉伯裔患者,均具有另一种独特的单倍型,这种单倍型在正常的德系犹太、伊拉克犹太和阿拉伯染色体中较为罕见。这些发现构成了德系犹太人、非德系犹太人和阿拉伯人共有的一种突变的首个实例,并且与II型突变起源于犹太人主要分支分化之前的一位奠基者相一致。我们的研究结果还表明,III型突变是在更近的时间出现在一名德系犹太个体中的。