Jouni Hayan, Shameer Khader, Asmann Yan W, Hazin Ribhi, de Andrade Mariza, Kullo Iftikhar J
Division of Cardiovascular Diseases, Mayo Clinic, Rochester, MN.
Division of Biomedical Statistics and Informatics, Mayo Clinic, Rochester, MN.
J Investig Med High Impact Case Rep. 2013 Oct 18;1(4):2324709613508932. doi: 10.1177/2324709613508932. eCollection 2013 Oct-Dec.
Although mosaic autosomal chromosomal abnormalities are being increasingly detected as part of high-density genotyping studies, the clinical correlates are unclear. From an electronic medical record (EMR)-based genome-wide association study (GWAS) of peripheral arterial disease, log-R-ratio and B-allele-frequency data were used to identify mosaic autosomal chromosomal abnormalities including copy number variation and loss of heterozygosity. The EMRs of patients with chromosomal abnormalities and those without chromosomal abnormalities were reviewed to compare clinical characteristics. Among 3336 study participants, 0.75% (n = 25, mean age = 74.8 ± 10.7 years, 64% men) had abnormal intensity plots indicative of autosomal chromosomal abnormalities. A hematologic malignancy was present in 8 patients (32%), of whom 4 also had a solid organ malignancy while 2 patients had a solid organ malignancy only. In 50 age- and sex-matched participants without chromosomal abnormalities, there was a lower rate of hematologic malignancies (2% vs 32%, P < .001) but not solid organ malignancies (20% vs 24%, P = .69). We also report the clinical characteristics of each patient with the observed chromosomal abnormalities. Interestingly, among 5 patients with 20q deletions, 4 had a myeloproliferative disorder while all 3 men in this group had prostate cancer. In summary, in a GWAS of 3336 adults, 0.75% had autosomal chromosomal abnormalities and nearly a third of them had hematologic malignancies. A potential novel association between 20q deletions, myeloproliferative disorders, and prostate cancer was also noted.
尽管作为高密度基因分型研究的一部分,镶嵌型常染色体异常被越来越多地检测到,但其临床相关性尚不清楚。在一项基于电子病历(EMR)的外周动脉疾病全基因组关联研究(GWAS)中,对数R比率和B等位基因频率数据被用于识别包括拷贝数变异和杂合性缺失在内的镶嵌型常染色体异常。对有染色体异常和无染色体异常患者的电子病历进行回顾,以比较临床特征。在3336名研究参与者中,0.75%(n = 25,平均年龄 = 74.8 ± 10.7岁,64%为男性)有异常强度图,提示常染色体异常。8名患者(32%)存在血液系统恶性肿瘤,其中4名同时患有实体器官恶性肿瘤,2名仅患有实体器官恶性肿瘤。在50名年龄和性别匹配但无染色体异常的参与者中,血液系统恶性肿瘤的发生率较低(2%对32%,P <.001),但实体器官恶性肿瘤的发生率无差异(20%对24%,P = 0.69)。我们还报告了每例观察到染色体异常患者的临床特征。有趣的是,在5例20号染色体长臂缺失的患者中,4例患有骨髓增殖性疾病,且该组中的3名男性均患有前列腺癌。总之,在一项对3336名成年人的GWAS中,0.75%有常染色体异常,其中近三分之一患有血液系统恶性肿瘤。还注意到20号染色体长臂缺失、骨髓增殖性疾病和前列腺癌之间可能存在新的关联。