Yan Qi, Chen Rui, Sutcliffe James S, Cook Edwin H, Weeks Daniel E, Li Bingshan, Chen Wei
Division of Pulmonary Medicine, Allergy and Immunology; Department of Pediatrics, Children's Hospital of Pittsburgh of UPMC, University of Pittsburgh, Pittsburgh, PA 15224, USA.
Department of Molecular Physiology &Biophysics, Vanderbilt Genetics Institute, Vanderbilt University Medical Center, Nashville, TN 37232, USA.
Sci Rep. 2016 Jun 22;6:28323. doi: 10.1038/srep28323.
Family-based sequencing studies have unique advantages in enriching rare variants, controlling population stratification, and improving genotype calling. Standard genotype calling algorithms are less likely to call rare variants correctly, often mistakenly calling heterozygotes as reference homozygotes. The consequences of such non-random errors on association tests for rare variants are unclear, particularly in transmission-based tests. In this study, we investigated the impact of genotyping errors on rare variant association tests of family-based sequence data. We performed a comprehensive analysis to study how genotype calling errors affect type I error and statistical power of transmission-based association tests using a variety of realistic parameters in family-based sequencing studies. In simulation studies, we found that biased genotype calling errors yielded not only an inflation of type I error but also a power loss of association tests. We further confirmed our observation using exome sequence data from an autism project. We concluded that non-symmetric genotype calling errors need careful consideration in the analysis of family-based sequence data and we provided practical guidance on ameliorating the test bias.
基于家系的测序研究在富集罕见变异、控制群体分层以及改善基因型分型方面具有独特优势。标准的基因型分型算法正确识别罕见变异的可能性较小,常常将杂合子错误地判定为参考纯合子。此类非随机错误对罕见变异关联检验的影响尚不清楚,尤其是在基于传递的检验中。在本研究中,我们调查了基因分型错误对基于家系序列数据的罕见变异关联检验的影响。我们进行了全面分析,以研究在基于家系的测序研究中使用各种实际参数时,基因型分型错误如何影响基于传递的关联检验的I型错误和统计效力。在模拟研究中,我们发现有偏倚的基因型分型错误不仅会导致I型错误膨胀,还会使关联检验的效力降低。我们使用来自一个自闭症项目的外显子序列数据进一步证实了我们的观察结果。我们得出结论,在分析基于家系的序列数据时,非对称基因型分型错误需要仔细考虑,并且我们提供了减轻检验偏倚的实用指导。