Fukui Kiyokazu, Kaneuji Ayumi, Kinoshita Eriko, Numata Yuhei, Nojima Takayuki, Matsumoto Tadami
Department of Orthopaedic Surgery, Kanazawa Medical University, 1-1 Daigaku, Uchinada-machi, Kahokugun, Ishikawa 920-0293, Japan.
Case Rep Orthop. 2013;2013:862935. doi: 10.1155/2013/862935. Epub 2013 Nov 10.
Pigmented villonodular synovitis is a rare, benign, but potentially locally aggressive disease that should be considered in younger patients who present with monoarticular joint symptoms and pathology. We present the case of a 33-year-old woman with a mass arising from her right hip joint that was examined using a multimodal radiological approach. Because her clinical presentation mimicked that of synovial osteochondromatosis of the hip, surgical dislocation was performed. Histopathological examination of the resected specimen confirmed the diagnosis of localized pigmented villonodular synovitis, with the mass consisting of proliferation of fibrohistiocytic cells, abundant hemosiderin, foamy histiocytes, and occasional giant cells. Because of the presence of tumor necrosis, we hypothesize that torsion of the tumor pedicle was the cause of acute presentation.
色素沉着绒毛结节性滑膜炎是一种罕见的良性疾病,但具有潜在的局部侵袭性,对于出现单关节症状和病理改变的年轻患者应予以考虑。我们报告一例33岁女性,其右髋关节出现肿物,采用多模态放射学方法进行检查。由于其临床表现与髋关节滑膜骨软骨瘤病相似,故进行了手术脱位。切除标本的组织病理学检查确诊为局限性色素沉着绒毛结节性滑膜炎,肿物由纤维组织细胞增生、大量含铁血黄素、泡沫状组织细胞及偶见的巨细胞组成。由于存在肿瘤坏死,我们推测肿瘤蒂扭转是急性表现的原因。